Paget's disease of bone is a debilitating condition affecting the skeletal system and sometimes presents with mono-ostotic pattern. A deformed bone is potential site for stress related injuries notably stress fracture. Diagnostic workup includes clinic-radiological co-relation with biochemical parameters and sometimes use of advanced imaging modalities. A mono-ostotic deformity of bone with thickened, coarse structure may warrant ruling out of this differential diagnosis. Early diagnosis and treatment including use of bisphosphonates have proved beneficial in recovery and good functional outcome.